Pediatr Allergy Respir Dis.  2012 Dec;22(4):428-432.

Congenital Bronchoesophageal Fistula with Imperforate Anus and Atrial Septal Defect in a 3-Year-Old Child

Affiliations
  • 1Department of Pediatrics, Institute of Allergy, Yonsei University College of Medicine, Seoul, Korea. kekim@yuhs.ac
  • 2Department of Diagnostic Radiology, Yonsei University College of Medicine, Seoul, Korea.
  • 3Division of Pediatric Surgery, Department of Surgery, Asan Medical Center, University of Ulsan College of Medicine, Seoul, Korea.

Abstract

Congenital bronchoesophageal fistula (BEF), congenital communication between esophagus and bronchus, is a rare malformation. Benign BEF shows only nonspecific symptoms that may delay a correct diagnosis and proper treatment. This is a case of a 3-year-old boy presenting congenital BEF with imperforate anus and atrial septal defect. He had recurrent pneumonia in the right lower lobe since he was 5 months old. A barium swallow examination showed a communicating fistula between the lower esophagus and the right lower lobe bronchus. Computed tomography scan supported to delineate the course of the fistula. He underwent resection surgery of the fistula and lobectomy of the right lower lobe. He recovered without any postoperative complications.

Keyword

Bronchoesophageal fistula; Imperforate anus; Atrial septal defect; Recurrent pneumonia

MeSH Terms

Anus, Imperforate
Barium
Bronchi
Child
Esophagus
Fistula
Heart Septal Defects, Atrial
Humans
Pneumonia
Postoperative Complications
Barium

Figure

  • Fig. 1 Chest radiography shows multifocal radiolucency in right lower lung field.

  • Fig. 2 Axial chest computed tomphy reveals unusual approximation between the right bronchus (white arrow) of pathologic area and the dilated air-contained esophagus (black arrow).

  • Fig. 3 Barium esophagogram demonstrates a fistula (arrow) from the lowesophagus leading to the right lower lobe.

  • Fig. 4 At dissection, an esophageal bronchus (inner circle) was found 5 mm in diameter and 30 mm in length.


Reference

1. Im JG, Lee WJ, Han MC, Chi JG, Han JK, Kim CW. Congenital broncho-oesophageal fistula in the adult. Clin Radiol. 1991. 43:380–384.
Article
2. Risher WH, Arensman RM, Ochsner JL. Congenital bronchoesophageal fistula. Ann Thorac Surg. 1990. 49:500–505.
Article
3. Kim JE, Rho JR. Congenital bronchoesophageal fistula: a report of one case. Korean J Thorac Cardiovasc Surg. 1979. 12:110–112.
4. Kim HM, Seo JH, Hong SJ, Moon HN, Hong CY, Park SI. Congenital bronchoesophageal fistula in a child. Pediatr Allergy Respir Dis. 1993. 3:144–150.
5. Hur J, Jang BH, Lee JT, Kim KT. Congenital bronchoesophageal fistula: two cases. Korean J Thorac Cardiovasc Surg. 1992. 25:194–199.
6. Lado Lado FL, Golpe Gómez A, Cabarcos Ortíz de Barrón A, Antúnez López JR. Bronchoesophageal fistulae secondary to tuberculosis. Respiration. 2002. 69:362–365.
Article
7. Spalding AR, Burney DP, Richie RE. Acquired benign bronchoesophageal fistulas in the adult. Ann Thorac Surg. 1979. 28:378–383.
Article
8. Murdock A, Moorehead RJ, Tham TC. Closure of a benign bronchoesophageal fistula with endoscopic clips. Gastrointest Endosc. 2005. 62:635–638.
Article
9. Park JH, Moon JH, Kim JH, Choi HJ, Lee JS, Hwang SC, et al. A case of tuberculous tracheoesophageal fistula. Korean J Intern Med. 1987. 32:690–695.
10. Smith DC. A congenital broncho-oesophageal fistula presenting in adult life without pulmonary infection. Br J Surg. 1970. 57:398–400.
Article
11. Braimbridge MV, Keith HI. Oesophago-bronchial fistula in the adult. Thorax. 1965. 20:226–233.
Article
12. Linnane BM, Canny G. Congenital broncho-esophageal fistula: a case report. Respir Med. 2006. 100:1855–1857.
Article
13. Kim JH, Park KH, Sung SW, Rho JR. Congenital bronchoesophageal fistulas in adult patients. Ann Thorac Surg. 1995. 60:151–155.
Article
14. Ramo OJ, Salo JA, Mattila SP. Congenital bronchoesophageal fistula in the adult. Ann Thorac Surg. 1995. 59:887–889.
Article
15. Aguilo R, Minguella J, Jimeno J, Puig S, Galeras JA, Gayete A, et al. Congenital bronchoesophageal fistula in an adult woman. J Thorac Cardiovasc Surg. 2006. 131:916–917.
Article
16. Zach MS, Eber E. Adult outcome of congenital lower respiratory tract malformations. Thorax. 2001. 56:65–72.
Article
17. Su L, Wei XQ, Zhi XY, Xu QS, Ma T. Congenital bronchoesophageal fistula in an adult: a case report. World J Gastroenterol. 2007. 13:3776–3777.
Article
18. Laforet EG. Treatment of esophagobronchial fistula. JAMA. 1978. 239:2338.
Article
19. Parry GW, Juma A, Dussek JE. Broncho-oesophageal fistula treated effectively without surgical resection. Thorax. 1993. 48:189–190.
Article
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