Tuberc Respir Dis.  2010 Feb;68(2):101-104. 10.4046/trd.2010.68.2.101.

Bronchopulmonary Sequestration with Dual Arterial Supply from Celiac Artery and Thoracic Aorta

• Kim WH
• Jeong SH
• Ha KW
• Lee WS
• Kim DC
• Chon GR

• KMID: 2050593
• DOI: http://doi.org/10.4046/trd.2010.68.2.101

Abstract

Bronchopulmonary sequestration (BPS) is a rare congenital malformation of the lower respiratory tract. Most intralobar BPSs are provided with an arterial blood via the thoracic or abdominal aorta but such a supply is rarely found in patients older than 50 years. We report a case of an intralobar BPS with a dual arterial supply from the celiac artery and thoracic aorta in a 50-year-old man presenting with a respiratory tract infection and haemoptysis. To our knowledge, this is the first case report of a BPS supplied by the celiac artery and thoracic aorta in a 50-year-old man.

Keyword

Bronchopulmonary Sequestration; Celiac Artery; Aorta, Thoracic

MeSH Terms

Aorta, Abdominal
Aorta, Thoracic
Bronchopulmonary Sequestration
Celiac Artery
Humans
Middle Aged
Respiratory System
Respiratory Tract Infections

Figure

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  Figure 1 Chest PA showed dense consolidation blurring the right cardiac border of the right lower lung field.

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  Figure 2 Chest CT showed an 8.0×7.8 cm mass in the right middle lobe, mainly and visible meandering arteries adjacent to heart (A). Air fluid level in the cysts of the right lower lobe suggested bronchiectasis (B).

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  Figure 3 3-D CT angiography showed meandering aberrant arteries (blue arrow) originated from celiac artery (A~C), and thoracic aorta (D).

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