J Korean Surg Soc.  2009 Jul;77(1):72-74. 10.4174/jkss.2009.77.1.72.

Xanthogranulomatous Cholecystitis Not Associated with Gallstone in a 9-year-old Girl

• Kim H
• Cho Y
• Park J

• KMID: 1464947
• DOI: http://doi.org/10.4174/jkss.2009.77.1.72

Abstract

Xanthogranulomatous cholecystitis (XGC) is known to be a rare, variant type of chronic cholecystitis and more frequently found in the adults with a prevalence of 0.7 to 13.2% of all cholecystitis, moreover very rare in children. Clinically, this usually presents as chronic or acute cholecystitis associated with gallstones, but biliary colic is unusual. Although it requires surgery for management, it may accompany some difficulties during cholecystectomy and postoperative complications such as biliary fistula. It could also give rise to higher conversion rates than other diseases of the gallbladder during laparoscopic procedures. We experienced a very rare pediatric case of xanthogranulomatous cholecystitis not associated with gallstones, successfully managed by laparoscopic cholecystectomy and hereby report it with literature reviews.

Keyword

Xanthogranulomatous cholecystitis; Child; Laparoscopic cholecystectomy

MeSH Terms

Adult
Biliary Fistula
Child
Cholecystectomy
Cholecystectomy, Laparoscopic
Cholecystitis
Cholecystitis, Acute
Colic
Gallbladder
Gallstones
Granuloma
Humans
Postoperative Complications
Prevalence
Xanthomatosis
Cholecystitis
Granuloma
Xanthomatosis

Figure

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  Fig. 1 Ultrasonography showed thickened gallbladder wall with intramural mass-like lesions.

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  Fig. 2 Pericholecystic fluid collection and intramural nodules at the liver bed in the computerized tomography of abdomen.

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  Fig. 3 T2 magnetic resonance imaging showed multiple intramural lesions in the gallbladder.

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  Fig. 4 Histologic finding confirms an infiltration of lymphocytes and plasma cell (H&E, ×200). (Inset) An aggregation of foamy histiocytes (arrow) characterizing the xanthogranulomatous cholecystitis (×400).

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